Osteofibrous Dysplasia-Like Adamantinoma of the Tibia Diagnosed at Age 6 Years Progressing into a Classic Adamantinoma over 39 Years, Reconstruction Performed by a Modified Capanna Technique: A Case Report
Osteofibrous Dysplasia-Like Adamantinoma of the Tibia Diagnosed at Age 6 Years Progressing into a Classic Adamantinoma over 39 Years, Reconstruction Performed by a Modified Capanna Technique: A Case Report作者机构:Orthopaedie Zentrum Zurich Seestrasse Zurich Switzerland Luzerner Kantonsspital Wolhusen Spitalstrasse Wolhusen Switzerland Kantonspital Baden Im Ergel Baden Switzerland Pathologikum Zurich Switzerland Zurich Switzerland Swissparc AG Zurich Switzerland
出 版 物:《Open Journal of Orthopedics》 (矫形学期刊(英文))
年 卷 期:2022年第12卷第7期
页 面:335-344页
学科分类:1002[医学-临床医学] 100214[医学-肿瘤学] 10[医学]
主 题:Osteofibrous Dysplasia-Like Adamantinoma Tibia Classic Adamantinoma Capanna Technique Pasteurized Autograft
摘 要:Background: It is generally accepted that there is a spectrum ranging from Osteofibrous Dysplasia (OFD) to Osteofibrous dysplasia-like Adamantinoma (OFD-AD) to “classic Adamantinoma (AD). However, it is controversial whether OFD may progress into OFD-AD and AD or these pathologic changes reflect sampling issues. We herein report the fifth case of late development of AD from OFD-AD to underline the importance of long-term follow-up. Case: At 6 years bone biopsy of the tibia revealed the diagnosis of OFD-AD, confirmed by repeat biopsies until the age of 18 years. At age 45 years a progressive focal osteolysis was biopsied and showed histologically a classic AD. The affected tibial diaphysis was resected and pasteurized. Reconstruction was performed adapting the “Capanna technique of inserting the ipsilateral mobilized fibula into the replanted autologous, pasteurized tibial segment as biologic stabilizer. At 1.5 years follow-up, the reconstruction has healed allowing full weight bearing.