Late contralateral recurrence of retinal detachment in incontinentia pigmenti:A case report
作者机构:Department of OphthalmologyThe First Affiliated Hospital of Guangxi Medical UniversityNanning 530021Guangxi ProvinceChina
出 版 物:《World Journal of Clinical Cases》 (世界临床病例杂志)
年 卷 期:2022年第10卷第13期
页 面:4171-4176页
核心收录:
学科分类:1002[医学-临床医学] 100212[医学-眼科学] 10[医学]
主 题:Incontinentia pigmenti Bilateral Retinal detachment Shift code mutation Vitrectomy Case report
摘 要:BACKGROUND Incontinentia pigmenti(IP)is a rare X-linked genetic *** mainly manifests as skin lesions and causes problems in the eyes,teeth,bones,and central nervous *** the various ocular manifestations,the most severe with difficult recovery is retinal detachment(RD).Here,we report an unusual case of bilateral asymmetrical *** SUMMARY We present the case of an 11-year-old Chinese girl with IP who complained of sudden blurring of vision in the left *** that time,she had been blind in her right eye for 4 *** with traction was observed in both eyes.A massive retinal proliferative membrane,exudation,and hemorrhage were seen in the left *** performed vitrectomy in her left *** visual acuity recovered to 20/50,and her retina had flattened within 2 d after *** the 3-mo follow-up,we performed retinal laser treatment of the non-perfused retinal area in her left ***,her visual acuity returned to 20/32,and no new retinal abnormalities *** In patients with IP with fundal abnormalities in one eye,it is important to focus on the rate of fundal change in the other *** in its early stages can be effectively treated with timely vitrectomy and laser photocoagulation.